| General population norma | Affected adult utility score (n = 48) | Parent utility score (n = 77) | |||||||||
---|---|---|---|---|---|---|---|---|---|---|---|---|
 | Mean | SD | Mean | SD | Difference | 95% CI | p-value | Mean | SD | Difference | 95% CI | p-value |
Overall | 0.86 | 0.24 | 0.56 | 0.28 | −0.30 | −0.38, −0.22 | < 0.001 | 0.80 | 0.19 | −0.06 | −0.10, − 0.02 | 0.007 |
Male | 0.88 | 0.16 | 0.64 | 0.21 | −0.24 | − 0.37, − 0.11 | 0.001 | 0.89 | 0.15 | 0.01 | −0.15, 0.17 | 0.877 |
Female | 0.85 | 0.18 | 0.53 | 0.30 | −0.32 | − 0.42, − 0.22 | < 0.001 | 0.79 | 0.19 | − 0.06 | − 0.11, − 0.01 | 0.010 |